Currarino triad with dual pathology in the presacral mass

Report of a case

C. R. Thambidorai, I. Muin, Razman Jarmin, A. Zulfiqar

Research output: Contribution to journalArticle

11 Citations (Scopus)

Abstract

PURPOSE: Currarino triad, which comprises anorectal stenosis, anterior sacral defect, and a presacral mass, is an uncommon cause of constipation in children and adults. The presacral mass in this triad is most often caused by an anterior sacral meningocele, a teratoma, or an enterogenous cyst, but rarely may be caused by dual pathology. A neonate with Currarino triad and dual pathology in the presacral mass is described in this report. METHOD: A male Chinese neonate, who presented with abdominal distention and constipation on the second day of life, was found to have features of Currarino triad. Colostomy was done in the neonatal period, and the presacral mass was excised by posterior sagittal perineal approach at the age of six months. RESULTS: The excised presacral mass consisted of an anterior meningocele and a teratoma. The patient continued to have constipation during follow-up and required anorectoplasty to correct residual anorectal stenosis. At the time of this report the patient was three years old and growing normally with normal anorectal function. DISCUSSION: Of a total of about 200 cases of complete Currarino triad found in the literature, in only 22 patients did the presacral mass contain both meningocele and teratoma. The features of these 22 patients and the current views on the surgical management of Currarino triad are discussed.

Original languageEnglish
Pages (from-to)974-977
Number of pages4
JournalDiseases of the Colon and Rectum
Volume46
Issue number7
DOIs
Publication statusPublished - 1 Jul 2003

Fingerprint

Meningocele
Pathology
Teratoma
Constipation
Newborn Infant
Colostomy
Cysts
Currarino triad
Anorectal Malformations

Keywords

  • Anorectal stenosis
  • Anterior meningocele
  • Constipation
  • Currarino triad
  • Sacral defect
  • Teratoma

ASJC Scopus subject areas

  • Gastroenterology

Cite this

Currarino triad with dual pathology in the presacral mass : Report of a case. / Thambidorai, C. R.; Muin, I.; Jarmin, Razman; Zulfiqar, A.

In: Diseases of the Colon and Rectum, Vol. 46, No. 7, 01.07.2003, p. 974-977.

Research output: Contribution to journalArticle

Thambidorai, C. R. ; Muin, I. ; Jarmin, Razman ; Zulfiqar, A. / Currarino triad with dual pathology in the presacral mass : Report of a case. In: Diseases of the Colon and Rectum. 2003 ; Vol. 46, No. 7. pp. 974-977.
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